◎ Investigational

Tominersen (RG6042)

2
Evidence entries
1
Clinical trials
Overview
Treatment Details
Mechanism of Action
An antisense oligonucleotide (ASO) delivered by intrathecal injection that binds HTT mRNA and triggers its degradation, reducing production of both mutant and normal huntingtin protein non-selectively. After an earlier Phase 3 trial (GENERATION HD1) was halted for lack of benefit at the studied dose/frequency, Roche is now evaluating a lower, less-frequent dosing regimen in younger patients with less disease burden in a new Phase 2 trial (GENERATION HD2).
Dosing Notes
Investigational; intrathecal (spinal) injection, dosing interval and amount under re-evaluation following the GENERATION HD1 trial.
Treatment Type
pharmaceutical
Clinical Evidence
What the Evidence Shows
Each finding below is linked to its primary source. Confidence levels reflect the quality and quantity of available evidence — not CelluTarget's endorsement of any treatment.
High: Supported by multiple robust studies or regulatory approval
Moderate: Supported by limited controlled studies or consistent case series
Low: Based on case reports, expert opinion, or early-phase data only
Low ConfidenceBased on case reports, expert opinion, or early-phase data only
Tominersen previously reduced levels of toxic mutant huntingtin protein in cerebrospinal fluid, but the Phase 3 GENERATION HD1 trial was halted after an interim analysis found no clinical benefit — and a signal of potential harm — at the studied dose and frequency. Roche is now testing a lower, less frequent dose in younger patients with less disease burden (GENERATION HD2).
Verified Jul 2026
Institutional Research
Huntington's disease: a therapeutic field on a bumpy ride
Published April 2026
View source ↗
The October 2025 Huntington's Disease Clinical Trials Update reports ongoing developments in Roche's tominersen programme within GENERATION HD2, following the earlier GENERATION HD1 outcome.
Verified Jul 2026
Peer Reviewed
Huntington's disease clinical trials update: October 2025 (Journal of Huntington's Disease)
Published November 2025
View source ↗
Clinical Trials
Linked Trials1 trial